Gupta, Varun, Noh, Ka-Won, Maschek, Hansjoerg, Thal, Stefan and Welter, Stefan ORCID: 0000-0002-4194-8215 (2022). A unique case of thoracic endometriosis syndrome and pulmonary Langerhans' cell histiocytosis: Six recurrent pneumothoraces. Respir. Med. Case Rep., 36. AMSTERDAM: ELSEVIER. ISSN 2213-0071

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Abstract

Spontaneous pneumothorax (SP) in women of reproductive age with causes such as thoracic endometriosis syndrome (TES) presents a diagnostic and therapeutic challenge. A 33-year-old women was treated conservatively with chest tube insertion for a first occurrence of a right-sided pneumothorax in September 2015. In January 2016, a right-sided video-assisted thoracoscopic surgery (VATS) wedge resection and partial parietal pleurectomy was performed due to a recurrence. A right-sided VATS was again performed in December 2016 with multiple wedge resections and a total pleurectomy revealing a pulmonary Langerhans' cell histiocytosis (PLCH) in the histological and immunohistochemical examinations. The patient was recommended an abstinence of smoking and further course was unremarkable until May 2019, when due to a recurrent pneumothorax, she received a talc pleurodesis via right-sided VATS. Due to yet another recurrence, she underwent a talc slurry pleurodesis over a right sided chest drain. In March 2020 due to recurrence, a right-sided VATS was performed and a blueish nodular lesion was resected from the diaphragm. The histological examination revealed an endometriosis with a diagnosis of TES. Since the patient did not exhibit a temporal relationship between her periods and the onset of pneumothorax symptoms, a final diagnosis of non-catamenial endometriosis-related pneumothorax was made. The patient is currently continuing smoking abstinence and is under hormone therapy. She has not presented with a recurrence. In clinical practice, it is important not to just relay on the information available to us, but to reevaluate the patient history to uncover new clues leading to a new diagnosis.

Item Type: Journal Article
Creators:
CreatorsEmailORCIDORCID Put Code
Gupta, VarunUNSPECIFIEDUNSPECIFIEDUNSPECIFIED
Noh, Ka-WonUNSPECIFIEDUNSPECIFIEDUNSPECIFIED
Maschek, HansjoergUNSPECIFIEDUNSPECIFIEDUNSPECIFIED
Thal, StefanUNSPECIFIEDUNSPECIFIEDUNSPECIFIED
Welter, StefanUNSPECIFIEDorcid.org/0000-0002-4194-8215UNSPECIFIED
URN: urn:nbn:de:hbz:38-670170
DOI: 10.1016/j.rmcr.2022.101603
Journal or Publication Title: Respir. Med. Case Rep.
Volume: 36
Date: 2022
Publisher: ELSEVIER
Place of Publication: AMSTERDAM
ISSN: 2213-0071
Language: English
Faculty: Unspecified
Divisions: Unspecified
Subjects: no entry
Uncontrolled Keywords:
KeywordsLanguage
CATAMENIAL PNEUMOTHORAX; WOMENMultiple languages
Respiratory SystemMultiple languages
URI: http://kups.ub.uni-koeln.de/id/eprint/67017

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